Daily Living Skills in Adolescent and Young Adult Males With Fragile X Syndrome

Angela John Thurman; Stephanie Summers Swinehart; Jessica Klusek; Jane E. Roberts; Lauren Bullard; Jocelyn Christina B. Marzan; W. Ted Brown; Leonard Abbeduto

doi:10.1352/1944-7558-127.1.64

Daily Living Skills in Adolescent and Young Adult Males With Fragile X Syndrome

Angela John Thurman, Stephanie Summers Swinehart, Jessica Klusek, Jane E. Roberts, Lauren Bullard, Jocelyn Christina B. Marzan, W. Ted Brown, Leonard Abbeduto

Research output: Contribution to journal › Article › peer-review

Abstract

By adulthood, most males with fragile X syndrome (FXS) require support to navigate day-to-day settings. The present study cross-sectionally: (1) characterized the profile of daily living skills in males with FXS and (2) examined associated participant characteristics (i.e., fragile X mental retardation protein [FMRP] expression, nonverbal cognition, language, autism symptomatology, and anxiety symptomatology) using the Waisman-Activities of Daily Living questionnaire. Males with FXS (n = 57, ages 15-23 years) needed more help/support in the areas of domestic and community daily livings skills, than in the area of personal daily living skills. Significant associations were observed between reduced daily living skills and lower nonverbal cognition, receptive language, expressive language, and increased autism symptomatology. Receptive language emerged as the strongest unique predictor of daily living skill performance.

Original language	English (US)
Pages (from-to)	64-83
Number of pages	20
Journal	American journal on intellectual and developmental disabilities
Volume	127
Issue number	1
DOIs	https://doi.org/10.1352/1944-7558-127.1.64
State	Published - Jan 1 2022
Externally published	Yes

Keywords

autism spectrum disorder
daily living skills
FMRP
fragile X syndrome
language

ASJC Scopus subject areas

Pediatrics, Perinatology, and Child Health
Neuropsychology and Physiological Psychology
Developmental and Educational Psychology
Arts and Humanities (miscellaneous)
Clinical Neurology
Psychiatry and Mental health

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10.1352/1944-7558-127.1.64

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Daily Living Skills in Adolescent and Young Adult Males With Fragile X Syndrome. / Thurman, Angela John; Swinehart, Stephanie Summers; Klusek, Jessica; Roberts, Jane E.; Bullard, Lauren; Marzan, Jocelyn Christina B.; Brown, W. Ted; Abbeduto, Leonard.

In: American journal on intellectual and developmental disabilities, Vol. 127, No. 1, 01.01.2022, p. 64-83.

Research output: Contribution to journal › Article › peer-review

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Daily Living Skills in Adolescent and Young Adult Males With Fragile X Syndrome

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Keywords

ASJC Scopus subject areas

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